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Overview and Recommendations
Background
- •Malignant hyperthermia (MH) is a pharmacogenetic disorder of skeletal muscle causing a life-threatening hypermetabolic crisis after exposure to volatile anesthetics or succinylcholine. The incidence is 0.18-3.9 per 100,000 general anesthesia procedures, with mortality falling from 70-80% in the 1960s to ≤10% with dantrolene availability.
- •The condition arises from uncontrolled calcium release from the sarcoplasmic reticulum via the ryanodine receptor type 1 (RYR1) in genetically predisposed individuals. Over 400 variants in RYR1 have been identified, with at least 34 causal; inheritance is autosomal dominant with incomplete penetrance (~40%).
- •MH susceptibility is diagnosed by genetic testing (RYR1, CACNA1S, STAC3) or the in vitro contracture test (IVCT). The European Malignant Hyperthermia Group 2025 guidelines introduced the MH genotype designation based on pathogenic variants.
- •Maladaptive calcium dysregulation drives the hypermetabolic state: ATP consumption accelerates, oxidative phosphorylation uncouples, and heat production skyrockets, leading to lactic acidosis, hyperkalemia, and rhabdomyolysis. Core temperature can rise >1°C every 5 minutes if untreated.
- •The clinical triad, hyperthermia, hypercarbia, and muscle rigidity, is the basis for early recognition. The provides a standardized retrospective definition, but treatment must begin on clinical suspicion alone.
Evaluation
- •Suspect MH in any patient under general anesthesia with volatile agents or succinylcholine who develops unexplained sinus tachycardia, rising end-tidal CO₂ despite increased minute ventilation, masseter spasm, or generalized muscle rigidity.
- •Ask about personal or family history of MH, unexplained hyperthermia during anesthesia, , or exertional heat illness. In children, inquire about congenital myopathies (central core disease, King-Denborough syndrome).
- •Examine for masseter spasm after succinylcholine, generalized rigidity, tachypnea, skin mottling, and dark urine. Early signs may be subtle; hyperthermia is often a late finding.
- •Order immediate arterial blood gas analysis to confirm metabolic acidosis (low pH, elevated lactate, base deficit). Also draw serum electrolytes (especially potassium), creatine kinase, and a coagulation panel.
- •Monitor core temperature continuously; end-tidal CO₂ monitoring is essential. The relative risk of death is 13.8-fold higher without core temperature monitoring.
- •Diagnostic criteria include the Larach clinical grading scale: score ≥35 indicates 'very likely' or 'almost certain' MH. However, do not delay treatment for scoring.
- •Also consider other causes of hypermetabolic state: , , , sepsis, . Differentiate by history of serotonergic drugs, antipsychotics, or thyroid disease.
- •After acute management, arrange for confirmatory testing of susceptibility: genetic testing for RYR1, CACNA1S, STAC3 as first line (sensitivity up to 70%). If negative and high suspicion remains, refer for IVCT.
- •In children, presenting signs vary by age: infants often present with hyperthermia, school-age children with masseter spasm, adolescents with hypercarbia and tachycardia. Adjust your index of suspicion accordingly.
Management
- •Call for help and activate the MH cart immediately. Discontinue all volatile anesthetics and succinylcholine; do not taper. Flush the circuit with 100% oxygen at 10-15 L/min.
- •Hyperventilate the patient with 100% oxygen to correct hypoxemia and eliminate residual volatile agent. Convert to a non-triggering anesthetic regimen (e.g., total intravenous anesthesia with propofol).
- •Administer 2.5 mg/kg IV rapidly based on actual body weight. Each vial contains 20 mg; reconstitute with 60 mL sterile water. Repeat every 5-10 minutes until physiologic signs (heart rate, ETCO₂, rigidity) normalize. The total dose may exceed 10 mg/kg in severe cases.
- •Initiate active cooling: apply ice packs to axillae, groin, and neck; infuse cold IV saline (4°C); consider gastric or bladder lavage with iced saline. Stop cooling once core temperature falls below 38.5°C to avoid overshoot.
- •Treat hyperkalemia: administer calcium gluconate 10-30 mg/kg IV or calcium chloride 10 mg/kg IV for cardiac protection. Follow with insulin 0.1 U/kg plus glucose 0.5 g/kg IV, and/or beta-agonists (e.g., albuterol). Monitor potassium closely.
- •Correct metabolic acidosis: hyperventilate to lower arterial CO₂; give sodium bicarbonate 1-2 mEq/kg IV if pH < 7.2. Follow with repeat ABG.
- •Monitor core temperature, ETCO₂, ABG, serum potassium, CK, and urine output (target >2 mL/kg/h to prevent myoglobinuric acute kidney injury). Maintain adequate hydration.
- •After the acute crisis, continue dantrolene 1 mg/kg IV every 4-6 hours for 24-48 hours to prevent recrudescence. Recrudescence occurs in ~14% of patients and carries a high mortality risk.
- •Avoid non-triggering drugs that may mimic or exacerbate MH: tramadol, meperidine, methadone, and fentanyl (serotonergic activity). Use morphine, non-opioid analgesics, and regional anesthesia for pain management.
- •For future anesthetics in MH-susceptible patients, use a trigger-free technique: avoid all volatile anesthetics and succinylcholine. Prepare the anesthesia machine by removing vaporizers, replacing the breathing circuit, and flushing with 10 L/min 100% oxygen for at least 60 minutes (or use activated charcoal filters for rapid washout).
- •Do not administer prophylactic dantrolene before anesthesia; it causes muscle weakness and is not indicated.
- •Refer the patient and first-degree relatives for definitive testing (genetic testing or IVCT) after recovery. All patients with a personal or family history of MH should be managed as susceptible until proven otherwise.
Board Review — High Yield
- •Masseter spasm after succinylcholine, may indicate MH susceptibility; 41% of such index cases are MH-positive.
- •End-tidal CO₂ rise, earliest sign of MH; often precedes hyperthermia; does not respond to increased minute ventilation.
- •Core temperature monitoring, mandatory for all general anesthetics >30 min; without it, mortality risk is 13.8-fold higher.
- •Dantrolene dose 2.5 mg/kg IV, based on actual body weight; repeat every 5-10 min; total dose may exceed 10 mg/kg.
- •Succinylcholine alone can trigger MH, 24 of 310 cases; stock dantrolene wherever succinylcholine is used.
- •Penetrance of RYR1 mutations is 40%, a previous uneventful anesthetic does not rule out future MH.
- •Children present differently, infants: hyperthermia; school-age: masseter spasm; adolescents: hypercarbia/tachycardia.
- •No prophylactic dantrolene, only trigger-free anesthesia (TIVA) is recommended for MHS patients.
- •Recrudescence in 14%, continue dantrolene 1 mg/kg q4-6h for 24-48 h post-crisis.
- •Genetic testing first line, sensitivity up to 70%; negative result does not exclude MH; IVCT remains gold standard.
Deep Dive — Evidence Details
Definition, Classification and Pain Phenotype
- ▸MH is a pharmacogenetic hypermetabolic reaction triggered by volatile anesthetics and succinylcholine, not a chronic pain condition.
- ▸The EMHG 2025 guidelines introduce the MH genotype as a new diagnostic category alongside the classic IVCT/CICR tests.
- ▸The Larach clinical grading scale provides a standardized retrospective definition, but treatment must begin on clinical suspicion alone.

Malignant hyperthermia (MH) is a pharmacogenetic disorder of skeletal muscle characterized by a life-threatening hypermetabolic reaction triggered by volatile anesthetics and succinylcholine [2]A1c[3]A1c[5]B3b[9]D5[15]B3b. Also called malignant hyperpyrexia or familial malignant hyperthermia, the condition arises from uncontrolled calcium release from the sarcoplasmic reticulum via the ryanodine receptor type 1 (RYR1) in genetically predisposed individuals [1]A1c[3]A1c.
Classification
MH susceptibility (MHS) is diagnosed by the in vitro contracture test (IVCT) or the calcium-induced calcium release (CICR) test, with the European Malignant Hyperthermia Group (EMHG) 2025 guidelines introducing a new diagnostic designation, the MH genotype, based on pathogenic variants in RYR1, CACNA1S, or STAC3 [2]A1c[3]A1c[9]D5. The Larach clinical grading scale provides a standardized tool for retrospective case definition, with a threshold of 45 points yielding a specificity of 90% and sensitivity of 59% [5]B3b. The clinical presentation is classified as a definite MH event when the Larach raw score exceeds 50, but treatment must begin immediately on suspicion without waiting for a formal score [3]A1c.
Pain Phenotype
MH is not a chronic pain condition and does not have a nociceptive, neuropathic, or nociplastic pain phenotype. The acute crisis itself produces severe muscle pain and rigidity due to sustained contraction and , but this is a symptom of the hypermetabolic state rather than a distinct pain syndrome. The therapeutic spine of MH management centers on aborting the hypermetabolic cascade with dantrolene, not on analgesic pathways [3]A1c.
Clinical Significance
MH is a medical emergency: the incidence is 0.18-3.9 per 100,000 general anesthesia procedures, and while mortality has fallen from 70-80% in the 1960s to ≤10% with dantrolene, rapid recognition and treatment remain essential [3]A1c. The next section details the molecular mechanisms, the RYR1 calcium channel dysregulation, that explain the clinical features described above.
Pearl: The Larach clinical grading scale provides a standardized retrospective definition, but treatment must begin on clinical suspicion alone.
Pathophysiology and Mechanism
- ▸MH is caused by uncontrolled calcium release from sarcoplasmic reticulum due to RYR1 (or CACNA1S) mutations, triggered by volatile anesthetics or succinylcholine.
- ▸The hypermetabolic cascade leads to hyperthermia, acidosis, hyperkalemia, and rhabdomyolysis; end-tidal CO2 rise is the earliest sign.
- ▸Chronic calcium leak in MHS patients causes myopathic symptoms even without anesthesia, and overlaps with exertional heat illness and rhabdomyolysis.
From this definition, the core pathophysiological event is an uncontrolled rise in myoplasmic calcium triggered by volatile anesthetics or succinylcholine [34]D5[35]D5. This cascade originates from a genetic defect in the skeletal muscle calcium release channel, the ryanodine receptor type 1 (RyR1), or less commonly the voltage-gated calcium channel Cav1.1 (encoded by CACNA1S) [21]D5[34]D5. Over 400 variants have been identified in the RYR1 gene, of which at least 34 are causal for MH; the prevalence of genetic abnormalities may be as high as 1 in 400 individuals [34]D5. Inheritance is autosomal dominant in humans [34]D5[35]D5. A third gene, STAC3, is also associated with MH susceptibility [21]D5.
The Calcium Release Cascade
Volatile anesthetics (halothane, sevoflurane, desflurane, isoflurane) and succinylcholine bind to the mutant RyR1, causing a sustained, uncontrolled release of Ca2+ from the sarcoplasmic reticulum into the myoplasm [24]D5[32]D5. This triggers a positive-feedback loop within excitation-contraction coupling: elevated myoplasmic Ca2+ activates further RyR1 opening, leading to a massive calcium overload [32]D5. The result is simultaneous activation of muscle contraction (rigidity) and metabolic machinery [34]D5.
Metabolic Consequences
The sustained calcium elevation drives hypermetabolism: ATP consumption accelerates, oxidative phosphorylation is uncoupled, and heat production skyrockets [25]C4[34]D5. Increased CO2 production outpaces ventilation, causing an early rise in end-tidal CO2 [34]D5. Anaerobic metabolism generates , while ATP depletion compromises membrane integrity, leading to hyperkalemia and [35]D5. The hypermetabolic state also increases oxygen consumption and produces a mixed respiratory and metabolic acidosis [29]D5. If untreated, core temperature can rise >1°C every 5 minutes, and rhabdomyolysis may cause acute kidney injury and life-threatening hyperkalemia [29]D5[34]D5.
Chronic Manifestations and Overlap Syndromes
Even in the absence of anesthetic triggers, MHS patients often experience myopathic symptoms due to a chronic RyR1 calcium leak [21]D5. This sustained leak increases mitochondrial electron transport chain activity, oxidative stress, and posttranslational RyR1 modifications that further impair calcium homeostasis [21]D5. MHS patients have impaired aerobic metabolism, with lower ATP production via oxidative pathways and reduced aerobic and anaerobic capacity compared to healthy controls [23]B3b. Exertional heat illness and exertional rhabdomyolysis share overlapping mechanisms with MH: all three are hypermetabolic states driven by uncontrolled intracellular calcium rise, high ATP demand, and oxidative stress [25]C4[32]D5. Transcriptomic studies show that MHS patients have downregulation of oxidative phosphorylation genes, while exertional heat illness patients upregulate inflammatory response genes, suggesting a common underlying pathophysiology [30]B3b.
These pathophysiological events produce the clinical triad of hyperthermia, hypercarbia, and muscle rigidity that form the basis for early recognition and acute management discussed in the following sections.
Pearl: The earliest sign of an MH crisis is an unexplained rise in end-tidal CO2 despite increased minute ventilation; this reflects the hypermetabolic state before hyperthermia develops [34]D5.
Epidemiology, Etiology and Risk Factors
- ▸MH incidence increased from 10.2 to 13.3 per million US hospital discharges (2000-2005), with prevalence across four states ranging 1.23-1.91 per 100,000 discharges.
- ▸Male sex is an independent risk factor (OR 2.37-3.49); RYR1 diagnostic mutations have incomplete penetrance (40.6%), and a previous uneventful anesthetic does not rule out future MH.
- ▸In-hospital mortality remains high (6.5%-16.9%), with lower mortality in children (0.7% vs 14.1% in adults).
From the molecular defect in the ryanodine receptor emerges an epidemiologic picture of a rare, sex-dependent, and incompletely penetrant disorder. The recorded incidence of MH in the United States rose from 10.2 to 13.3 cases per million hospital discharges between 2000 and 2005, a statistically significant increase [45]C4. Across four US states, the prevalence per 100,000 hospital discharges ranged from 1.23 (95% CI 0.80-1.66) in New York to 1.91 (95% CI 1.48-2.34) in California; among surgical inpatients, prevalence reached 2.86 per 100,000 surgical discharges in Florida (95% CI 2.00-3.71) [55]B3b. In Japan, 17 MH reactions were identified among 1,238,171 general anesthesia procedures, a rate of approximately 1.4 per 100,000 [48]D5. The estimated annual number of MH events in US ambulatory surgery centers is 47 [49]D5.
Demographic Distribution
MH can occur at any age. The median age of affected patients in a US nationwide sample was 39 years (interquartile range 23-54), and children (≤18 years) accounted for only 17.8% of cases [45]C4. Pediatric series from North America (264 cases) and Japan (187 cases) demonstrate that clinical features vary by age group, but the condition is not confined to infancy or childhood [42]B3b[43]B3b.
Sex is a strong independent risk factor. Males are substantially more likely to develop MH. In a multicenter case-control study of RYR1 mutation carriers, the odds ratio for males versus females was 2.37 (95% CI 1.36-4.12) [44]B3b. A Japanese database study reported a similar male predominance (OR 3.49) [48]D5.
Risk Factors
| Factor | OR/RR/HR (95% CI) | Plain-English Meaning | Independent? | Reference |
|---|---|---|---|---|
| Male sex | OR 2.37 (1.36-4.12) | Males have about 2.4 times the odds of developing MH compared with females | Yes | [44]B3b |
| Male sex | OR 3.49 (1.14-10.7) | Males have about 3.5 times the odds (consistent finding) | Yes | [48]D5 |
| RYR1 diagnostic mutation | Penetrance 40.6% (93/229) | 4 in 10 carriers will develop MH on exposure; previous uneventful anesthesia does not rule out risk | Yes (genetic) | [44]B3b |
| Increasing age | Associated with higher in-hospital mortality, not incidence | Older patients who develop MH are more likely to die | Yes (mortality risk) | [45]C4 |
| Female sex | Associated with higher mortality (14.1% vs 0.7% in children) | Females who develop MH have worse outcomes | Yes (mortality risk) | [45]C4 |
| Comorbidity burden | Higher Charlson index → increased mortality | Sicker patients fare worse | Yes (mortality risk) | [45]C4 |
Genetic Etiology and Penetrance
MH is a pharmacogenetic disorder with an autosomal dominant inheritance pattern in most families. Mutations in the ryanodine receptor 1 gene (RYR1) account for approximately half of cases [44]B3b. The overall penetrance of nine diagnostic RYR1 mutations was 40.6% (93 of 229 genotype-positive individuals), with no statistical difference among the specific mutations [44]B3b. Importantly, the likelihood of developing MH on exposure to trigger agents among all RYR1 mutation carriers was 0.25, but among probands (survivors of a previous MH reaction) it rose to 0.76 (95% CI of the difference 0.41-0.59) [44]B3b. This reinforces that a previous uneventful anesthetic does not preclude the possibility of developing MH [44]B3b. The median age of probands was 12 years (interquartile range 6-32.5) [44]B3b.
Associated Conditions
Exertional heat illness, exertional , and idiopathic hyperCKemia have been associated with MH susceptibility, although the evidence for a causal relationship is weak [25]C4[50]D5[52]C4. In one series of 37 subjects with idiopathic hyperCKemia, in vitro contracture testing identified only one MH-susceptible and one MH-equivocal individual [50]D5. The Malignant Hyperthermia Association of the United States recommends that patients with a history of unexplained exertional heat illness or rhabdomyolysis be considered for MH workup, but controlled clinical studies supporting this are lacking [25]C4.
Temporal Trends in Mortality
Despite increased awareness, MH mortality remains substantial. In-hospital mortality in the United States between 2000 and 2005 ranged from 6.5% to 16.9% per year (P<0.0001) [45]C4. In a four-state analysis, 11% of patients with a recorded MH diagnosis died on discharge [55]B3b. In the Japanese pediatric cohort, overall mortality was 15.5%, but declined to 8.8% in the period 2000-2020 [42]B3b. Children had lower mortality than adults (0.7% vs 14.1%, P<0.0001) [45]C4.
These epidemiologic patterns, the rarity of the disorder, the male predominance, the incomplete penetrance of RYR1 mutations, and the persistent mortality, inform the clinical vigilance needed when volatile anesthetics or succinylcholine are used. The next section details the signs and symptoms that should trigger immediate recognition of an MH crisis.
Pearl: In-hospital mortality remains high (6.5%-16.9%), with lower mortality in children (0.7% vs 14.1% in adults).
Clinical Presentation
- ▸The initial clinical sign of MH varies by age: elevated temperature in infants, masseter spasm in children aged 2-12 yr, and rising ETCO₂ in adolescents [42].
- ▸Penetrance of RYR1 mutations is incomplete (40.6%) and sex-dependent; males have higher odds of developing MH (OR 2.37) [44].
- ▸Treatment delay is directly linked to morbidity; a 50‑min delay is associated with 100% complication rate [59].
The clinical features of malignant hyperthermia are as heterogeneous as the genetic mutations that underlie it, with age, sex, and the type of anesthetic exposure influencing the early presentation [42]B3b[44]B3b.
Symptoms
Patient-reported symptoms are rare because MH typically emerges during general anesthesia. In the prodromal phase after succinylcholine, the awake patient may describe muscle fasciculations, jaw pain, or palpitations. Masseter spasm may be reported as difficulty opening the mouth. In children, the first recognized manifestation (often noted by the parent or clinician) is elevated temperature (46.7% in the 0-24 month age group) or generalized muscular rigidity (26.7%) [42]B3b. In older children (2-12 yr), masseter spasm (35.0%) and generalized rigidity (19.5%) predominate; in adolescents (13-18 yr), a rising end-tidal CO₂ (26.5%) and tachycardia (22.4%) are the earliest clues [42]B3b.
Signs
Physical examination and monitoring reveal a constellation of findings that cluster by organ system:
- Cardiovascular: Sinus tachycardia is the most common sign. Arrhythmias, hypotension, and eventually cardiac arrest may follow.
- Respiratory: Tachypnea, an unexplained increase in end-tidal CO₂ despite high minute ventilation, and .
- Musculoskeletal: Masseter spasm, generalized muscle rigidity, (elevated creatine kinase, myoglobinuria, dark urine). Dark urine was noted in 75.5% of the middle pediatric cohort (2-12 yr) [42]B3b.
- Metabolic: Hyperthermia is often a late sign; metabolic acidosis, hyperkalemia, and occur as the crisis progresses.
- Laboratory: Peak CK is highest in the 2-12 yr group [42]B3b. Myoglobinuria, DIC, and elevated lactate are common in fulminant cases.
Onset and Progression
Tachycardia and rising ETCO₂ are often the earliest signs, appearing within minutes of trigger exposure [63]A1c. Masseter spasm may occur immediately after succinylcholine [64]A1c. Hyperthermia is a late sign, and treatment delay increases complications every 10 min, reaching 100% at a 50-min delay [59]B2a. Modern agents (desflurane, sevoflurane, isoflurane) can cause a delayed onset of several hours [68]D5.
Phenotypic Variants
| Variant | Description | Key Features |
|---|---|---|
| Fulminant MH | Classic hypermetabolic crisis | Rapid onset, high fever, rigidity, rhabdomyolysis, DIC [63]A1c |
| Abortive MH | Incomplete syndrome | Masseter spasm, mild metabolic changes, no hyperthermia [64]A1c |
| Delayed-onset MH | Onset >1 h after trigger | More common with modern agents, may be less severe [68]D5 |
| MH-like syndrome in DMD | Rhabdomyolysis without true MH susceptibility | Hyperkalemia, cardiac arrest; avoid succinylcholine [70]D5 |
| Isolated masseter spasm | Jaw rigidity after succinylcholine | May indicate MH susceptibility or a variant [64]A1c |
Red Flags
- Masseter spasm (especially after succinylcholine) [64]A1c
- Unexplained tachycardia, tachypnea, or rising ETCO₂ [63]A1c
- Metabolic acidosis disproportionate to respiratory effort
- Hyperthermia (rectal >38.8 °C) [63]A1c
- Failure of CO₂ to decrease with increased minute ventilation
Atypical Presentations
- MH without hyperthermia (early or abortive forms)
- Postoperative rhabdomyolysis (e.g., in Duchenne muscular dystrophy) [70]D5
- Recurrent MH after initial treatment, requiring ongoing dantrolene [64]A1c
Pearl: The earliest signs of MH, tachycardia and rising ETCO₂, are often subtle; a high index of suspicion is required, especially in young males with succinylcholine exposure, as every 10-minute delay in dantrolene administration increases complication risk [59]B2a.
| Age Group | Most Common Initial Sign | Frequency |
|---|---|---|
| 0-24 mo | Elevated temperature | 46.7% [42]B3b |
| 2-12 yr | Masseter spasm | 35.0% [42]B3b |
| 13-18 yr | Elevated end‑tidal CO₂ | 26.5% [42]B3b |
Diagnosis and Workup
- ▸Genetic testing of RYR1, CACNA1S, and STAC3 is the first-line test for MH susceptibility, with sensitivity up to 70%.
- ▸The in vitro contracture test (IVCT) remains the gold standard when genetic testing is inconclusive, but the calcium wave frequency assay (92% sensitivity, 88% specificity) is an emerging alternative.
- ▸Clinical diagnosis of acute MH relies on a constellation of signs (tachycardia, hypercarbia, rigidity, rising temperature, metabolic acidosis) and the MH clinical grading scale (score ≥ 35 indicates very likely MH).
The clinical features described above should trigger immediate intervention, but the definitive diagnosis of MH susceptibility relies on laboratory confirmation. The approach to diagnosis differs between the acute crisis and the subsequent determination of susceptibility, and each requires a distinct stepwise algorithm.
Clinical Diagnosis of Acute MH
During an evolving MH reaction, diagnosis is based on a constellation of clinical signs and laboratory abnormalities, not a single test. The European Malignant Hyperthermia Group guidelines provide a recognition box that includes sinus tachycardia, hypercarbia (end-tidal CO₂ > 55 mm Hg), masseter or generalised muscle rigidity, rapidly rising temperature (> 38.8 °C), tachypnoea, and metabolic acidosis [63]A1c. The Association of Anaesthetists 2020 guideline emphasises that early features, tachycardia, hypercarbia, and rising end-tidal CO₂ despite increased minute ventilation, are more sensitive than fever [40]A1c.
Table 1. Key Clinical and Laboratory Features of Acute MH
| Feature | Finding |
|---|---|
| Sinus tachycardia | Present in 73.1% of paediatric cases [43]B3b |
| Hypercarbia | End-tidal CO₂ > 55 mm Hg in 68.6% [43]B3b |
| Rapid temperature increase | > 0.5 °C per 15 min; peak temperature > 38.8 °C in 48.5% [43]B3b |
| Masseter spasm | More common in children aged 2-12 yr [43]B3b |
| Metabolic acidosis | Low pH, elevated lactate, base deficit |
| Hyperkalemia | Peak K⁺ higher in older children [43]B3b |
| Elevated creatine kinase | Often > 10,000 U/L |
| Myoglobinuria | Tea-coloured urine |
The MH clinical grading scale assigns points for each feature; a score ≥ 35 indicates a “very likely” or “almost certain” MH event [43]B3b. This tool is useful for retrospective classification and research but should not delay treatment.
Laboratory Studies
Once the crisis is suspected, immediate arterial blood gas analysis is essential to confirm metabolic acidosis, and serum electrolytes (especially potassium), creatine kinase, and a coagulation panel should be drawn. Hyperkalemia is a leading cause of cardiac arrest during MH. Peak potassium values are higher in older children and adults [43]B3b. After the acute event, serial CK measurements are followed until they peak and decline; a CK > 10,000 U/L is suggestive.
Genetic Testing
Genetic testing of the three known MH-associated genes, RYR1, CACNA1S, and STAC3, has become the first line of testing for MH susceptibility, with sensitivity up to 70% [10]D5. The American Society of Anesthesiologists and Canadian Anesthesiologists' Society endorse a stepwise approach that uses clinical history and variant interpretation [10]D5. Pathogenic or likely pathogenic variants in RYR1 are found in ~50-70% of MH-susceptible families. Exome sequencing can identify asymptomatic patients at risk [82]D5. However, the absence of a known pathogenic variant does not exclude susceptibility; contracture testing may be needed [10]D5.
Table 2. Performance of Diagnostic Tests for MH Susceptibility
| Test | Sensitivity | Specificity | Notes |
|---|---|---|---|
| Genetic testing (RYR1/CACNA1S/STAC3) | Up to 70% [10]D5 | High for known pathogenic variants [79]D5 | First-line; negative result does not rule out MH |
| In vitro contracture test (IVCT) | Considered gold standard; exact sensitivity not reported in this dataset | Gold standard but limited by requirement for fresh muscle biopsy [78]D5 | Used when genetic testing is inconclusive |
| Calcium wave frequency assay (CaWFa) | 92% [78]D5 | 88% [78]D5 | Emerging test on single muscle fibers; minimally invasive |
In Vitro Contracture Testing
The in vitro contracture test (IVCT) remains the gold standard for diagnosing MH susceptibility, but it requires an open muscle biopsy (typically 2 g of vastus lateralis) and must be performed at a specialised centre [78]D5. The test measures the contractile response of muscle strips to halothane and caffeine. The IVCT has high sensitivity but suffers from limited availability, invasiveness, and the need for fresh tissue [78]D5.
Emerging Diagnostic Tests
The calcium wave frequency assay (CaWFa) is a novel test that uses a 50 mg muscle segment to measure regenerative calcium waves in single fibers exposed to halothane. At a threshold of 1 mM halothane with a wave frequency of 1.57 waves/min, it achieved 92% sensitivity and 88% specificity, comparable to the IVCT [78]D5. This test offers a potentially less invasive alternative, though it is not yet widely available.
Stepwise Workup Algorithm
For suspected acute MH event:
- Recognize clinical signs (tachycardia, hypercarbia, rigidity, rising temperature, metabolic acidosis).
- Discontinue volatile anaesthetics and succinylcholine; administer 100% oxygen.
- Give 2.5 mg/kg IV rapidly.
- Obtain arterial blood gas, serum K⁺, CK, and coagulation studies.
- After stabilisation, arrange for confirmatory testing of susceptibility.
For MH susceptibility evaluation (elective):
- Obtain detailed personal and family history of anaesthetic complications.
- Proceed with genetic testing of RYR1, CACNA1S, and STAC3 [10]D5.
- If genetic testing identifies a pathogenic or likely pathogenic variant, the patient is diagnosed as MH-susceptible.
- If genetic testing is negative or inconclusive and clinical suspicion remains high, refer for IVCT [10]D5.
- Consider CaWFa if available and IVCT is not feasible [78]D5.
Pearl: The diagnosis of MH susceptibility is confirmed by genetic testing or contracture testing; however, a negative genetic test does not rule out susceptibility, contracture testing should be considered in high-risk individuals [10]D5.
Controversies and Guideline Disagreement
| Question | Position A | Position B | Strength | Implication |
|---|---|---|---|---|
| Should unselected populations be screened for RYR1 variants? | Genomic screening can identify asymptomatic patients at risk [82]D5 | Low frequency of classic hypermetabolic phenotypes in unselected RYR1 variant carriers [79]D5 | Weak; insufficient evidence for population screening | Current guidelines recommend testing only for those with personal or family history of MH [40]A1c |
| Is IVCT still the gold standard? | Yes; IVCT is the accepted standard [78]D5 | Genetic testing is now first line, with IVCT reserved for inconclusive cases [10]D5 | Moderate shift | Many centres now use genetic testing first, reducing the need for invasive biopsies |
Severity, Staging and Perioperative Risk Stratification
- ▸Penetrance of RYR1 mutations is incomplete (40.6%) and sex-dependent (50% in males vs 29.7% in females); previous uneventful anesthesia does not exclude MHS [44].
- ▸The Larach Clinical Grading Scale classifies reaction severity but is not highly sensitive (55.8% of confirmed reactions score ≥35) [10].
- ▸A genetic risk stratification algorithm incorporating personal/family history and variant pathogenicity (including VUS-Hi) guides whether to use trigger-free anesthesia [10].
Once the diagnosis of malignant hyperthermia susceptibility (MHS) is established, the clinical picture is stratified by reaction severity, penetrance of the underlying genetic variant, and the perioperative risk of triggering a crisis. Unlike many diseases, MH has no formal staging system; instead, the Larach Clinical Grading Scale (CGS) provides a validated severity score for a given reaction. Points are assigned for muscular rigidity, , hyperthermia, cardiac involvement, and family history, yielding a rank from "somewhat less than likely" to "almost certain", a score of 20-34 points is "somewhat greater than likely," 35-49 is "very likely," and ≥50 is "almost certain" [10]D5. However, CGS is not highly sensitive; in one study, only 55.8% of confirmed MH reactions scored ≥35, often because of missing data or early (aborted) treatment [10]D5.
Penetrance and Risk Factors
Penetrance of diagnostic RYR1 mutations is incomplete and sex-dependent. Among 229 carriers of nine diagnostic RYR1 mutations, overall penetrance was 40.6% (93 of 229), with no significant differences among mutations [44]B3b. Males had significantly higher penetrance than females (50% vs 29.7%; P = 0.002), and the odds of developing MH on exposure were 2.37 (95% CI, 1.36-4.12) in males [44]B3b. The proband's median age at first reaction was 12 years (interquartile range 6-32.5 years), and penetrance increased with younger age and more potent triggering agents. These data reinforce the critical point: a previous uneventful anesthetic does not rule out MHS [44]B3b.
Specific RYR1 variants differ in the severity of the resulting phenotype. Variants located at conserved sites or in the Bsol domain of RYR1 produce more severe laboratory and clinical contracture responses and are associated with shorter onset time and higher peak CK [83]D5 [7]C4. The mutation type directly influences the risk of exercise-induced and heat stroke, which in turn serve as clinical markers of MHS severity [25]C4.
Genetic Risk Stratification for Perioperative Decision-Making
The North American approach to perioperative risk stratification integrates genetic testing results with personal and family history [10]D5. The decision algorithm (Figure 1 of [10]D5) starts with three questions:
- Does the patient have a personal history of MH, hyperCKemia, or ≥2 episodes of exertional heat illness?
- Does a family member have MHS or a documented MH reaction?
- Has the patient or a family member undergone genetic testing, and what is the result?
Pathogenic, likely pathogenic, and VUS-Hi (variant of uncertain significance - high-range) variants are treated as indicating MHS, whereas VUS-Mid, VUS-Lo, likely benign, and benign variants in a patient with no personal or family history do not confer increased risk [10]D5. The threshold for action is deliberately lowered because the consequences of a missed MHS are devastating, while avoiding trigger agents is straightforward [10]D5. For patients with a positive family history but no personal history, full sequencing of RYR1, CACNA1S, and STAC3 is recommended; if the familial diagnostic variant is found, the patient is managed as MHS [10]D5. If no variant is identified, the patient is not at elevated risk.
Risk of Mortality and Complications
Despite improved recognition and dantrolene availability, mortality remains substantial. In a 2007-2012 North American Malignant Hyperthermia Registry analysis, the death rate from MH was 9.5% (8 of 84 events), and the cardiac arrest rate was 8.3% (7 of 84, with no successful resuscitations) [92]D5. The relative risk of death was 13.8 (lower limit 2.1) when no temperature monitoring was used and 9.7 (1.5) with skin temperature monitoring compared with core temperature monitoring [92]D5. Longer anesthetic exposure before dantrolene administration was associated with higher peak temperatures (P = 0.00056) [92]D5. These data underscore that severity stratification is not merely academic, it directly affects survival. The ASA and MHAUS now recommend core temperature monitoring for all general anesthetics lasting ≥30 minutes [92]D5.
Pearl: The most actionable risk stratification tool is the combination of personal/family history and genetic results: a VUS-Hi variant without clinical history should still be treated as MHS, because the cost of false-positive avoidance, a nontriggering anesthetic, is far lower than the cost of a missed true-positive reaction [10]D5.
Controversies and Guideline Disagreement
| Question | Position A (North America) | Position B (EMHG) | Strength | Implication |
|---|---|---|---|---|
| Role of contracture testing | CHCT is largely unavailable; genetic testing is primary [10]D5 | IVCT remains the gold standard for definitive diagnosis [10]D5 | Disagreement reflects resource availability | North American algorithm relies on genotype + history; EMHG still recommends IVCT for discordant cases |
| Threshold for VUS management | VUS-Hi treated as MHS; VUS-Mid/Lo not [10]D5 | Typically only pathogenic/likely pathogenic variants acted upon [10]D5 | North America intentionally lowers threshold | May increase false-positive rate but reduces risk of missed MHS |
Perioperative Anesthetic Conduct: Airway Management, Technique Selection and Intraoperative Care
- ▸Anesthesia workstation preparation for MHS patients requires either prolonged flushing with component replacement (Dräger Primus: autoclaved diaphragm and breathing system, 5 min flush at 10 L/min) or activated charcoal filters (Dräger Zeus: M3 method achieves instantaneous washout).
- ▸Succinylcholine remains indicated for emergency airway rescue despite its MH-triggering potential; the SAMBA position statement supports its use in class B facilities without dantrolene, but dantrolene should be immediately available when succinylcholine is used.
- ▸Higher-performing anesthesia teams in simulated MH crises demonstrate more situation assessment and less task distribution, supporting the use of cognitive aids and simulation training.
Once risk stratification identifies a patient as malignant hyperthermia-susceptible (MHS) or the clinical scenario demands a trigger-free anesthetic, the conduct of anesthesia shifts from routine to a deliberate, protocol-driven process. Three axes define this phase: preparing the anesthesia workstation to eliminate volatile agent contamination, selecting a non-triggering anesthetic technique, and maintaining heightened vigilance through emergence and recovery.
Anesthesia Workstation Preparation
Volatile anesthetics adsorb to internal machine components and can persist at clinically relevant concentrations even after the vaporizer is turned off. The Malignant Hyperthermia Association of the United States (MHAUS) recommends flushing the workstation at 10 L/min fresh gas flow for a minimum of 20 minutes before use in an MHS patient, but this alone is often insufficient. In a study of the Dräger Primus workstation, washout of isoflurane to <5 ppm required 67 ± 6.5 minutes with no component replacement, but fell to 3.2 ± 0.4 minutes when both the ventilator diaphragm and integrated breathing system were replaced with autoclaved components [95]D5. The authors recommend replacing these parts, flushing for 5 minutes at 10 L/min, and maintaining that flow for the duration of anesthesia [95]D5.
For Dräger Zeus anesthesia workstations, three preparation methods have been systematically compared [90]D5:
| Method | Description | Time to <5 ppm (high-flow phase) | Peak rebound concentration (low-flow phase) | Estimated cost per case (including OR time) |
|---|---|---|---|---|
| M1 | Change disposables (circuit, soda lime, CO₂ line, water traps) | 88 min (95% CI 69-112) | 15 ppm | $2670 |
| M2 | M1 + replace breathing system with autoclaved one | 11 min (95% CI 9-15) | 6 ppm | $969 |
| M3 | M1 + mount 2 activated charcoal filters on respiratory limbs | Instantaneous (<1 ppm) | 1 ppm | $360 |
M3 is the most rapid and cost-effective when operating room (OR) time is valued, though anesthetic concentration rises 33-fold (95% CI 21-50) after filter removal, so filters must remain in place until the patient is disconnected [90]D5. Institutions with surplus OR capacity may opt for M1, but M3 is preferred when demand exceeds capacity [90]D5.
Airway Management and Succinylcholine
Difficult airway management is more common in certain MHS-associated conditions. Children with have higher odds of difficult IV access (OR 7.1, 95% CI 1.81-27.90) and difficult airway management (OR 4.06, 95% CI 1.01-16.39) compared with controls [76]C4. The anesthesia team should prepare for these challenges with advanced airway equipment and ultrasound-guided vascular access.
Succinylcholine is a known trigger of MH, yet it remains the drug of choice for emergency airway rescue in the “cannot intubate, cannot ventilate” scenario. The Society for Ambulatory Anesthesia (SAMBA) position statement argues that in class B ambulatory facilities where no volatile anesthetics are used and dantrolene is not stocked, the morbidity and mortality from exceeds the risk of succinylcholine-triggered MH [91]D5. However, a case report of a 6-year-old boy who developed an awake MH-like reaction after succinylcholine (without prior volatile exposure) underscores that the drug can precipitate fulminant MH even in the absence of inhalational agents [86]C4. The clinician must weigh these risks: succinylcholine should be reserved for true emergencies, and when used, dantrolene must be immediately available.
Anesthetic Technique Selection
Total intravenous anesthesia (TIVA) is the cornerstone of trigger-free anesthesia for MHS patients. Propofol and remifentanil have been used safely in patients with central core disease undergoing cesarean section, avoiding both volatile agents and succinylcholine [96]C4. No single drug has been statistically significantly associated with MH occurrence in large database studies; sevoflurane and rocuronium showed a non-significant trend toward higher prevalence [48]D5. The practical rule remains: avoid all volatile anesthetics and succinylcholine in known or suspected MHS patients. Propofol, opioids, benzodiazepines, ketamine, and non-depolarizing neuromuscular blockers (except possibly rocuronium, though evidence is reassuring) are safe.
Intraoperative Monitoring
Standard monitoring (ECG, noninvasive blood pressure, , , temperature) is mandatory. Capnography is particularly sensitive: a negative arterial-to-end-tidal CO₂ gradient ([a-ET]Pco₂ < 0) has been described as an early sign of MH during desflurane anesthesia, reflecting increased CO₂ production and cardiac output [99]C4. This gradient can serve as a diagnostic and monitoring tool during crisis [99]C4.
Team coordination during an MH crisis is a learned skill. In simulated MH scenarios, higher-performing anesthesia crews exhibited significantly less task distribution (β = -0.539, P < 0.01) and significantly more situation assessment (β = 0.569, P < 0.05) compared with lower-performing crews [93]B3b. Lower-scoring crews were more likely to split into subcrews without maintaining a shared plan [93]B3b. These findings support the use of cognitive aids, closed-loop communication, and regular simulation training to improve crisis management.
Emergence and Recovery
MH can manifest in the post-anesthesia care unit (PACU) after an uneventful intraoperative course, particularly with desflurane where delayed onset has been reported [99]C4. Temperature and end-tidal CO₂ monitoring should continue into recovery. The anesthesia workstation must remain prepared for immediate use if a crisis develops. The transition to the next section, acute management and crisis pathways, begins the moment any sign of hypermetabolism appears.
Pearl: For Dräger Zeus workstations, mounting two activated charcoal filters (M3) achieves instantaneous volatile washout to <1 ppm and is the most cost-effective method when OR time is valued; filters must remain in place until the patient is disconnected to avoid a 33-fold rebound [90]D5.
Acute Management and Crisis Pathways
- ▸Immediate trigger removal and dantrolene administration are the cornerstones of acute MH management; delay increases morbidity linearly with time [59].
- ▸Core temperature monitoring reduces mortality risk; skin temperature monitoring is inadequate, and end-tidal CO₂ is the worst predictor of survival [92].
- ▸Recrudescence occurs in 14.4% of patients, mandating continued dantrolene and ICU monitoring for 24-48 hours [43].
Once the diagnosis of malignant hyperthermia (MH) is suspected based on the clinical signs described in the preceding section, the clinician must act immediately with a coordinated crisis response. Every minute of delay increases morbidity; treatment delay increases complications with each 10-minute interval, reaching 100% at 50 minutes [59]B2a.
Immediate Actions and Trigger Removal
- Call for help and activate the MH cart. Notify the surgeon to conclude or abort the procedure as soon as possible.
- Discontinue all volatile anesthetics and succinylcholine immediately. Do not waste time tapering, turn off the vaporizer and flush the circuit with 100% oxygen at 10-15 L/min.
- Hyperventilate with 100% oxygen to correct hypoxemia and rapidly eliminate residual volatile agent.
- Convert to a non-triggering anesthetic regimen (e.g., total intravenous anesthesia with propofol) [62]A1c.
Dantrolene Administration
Dantrolene is the only specific antidote for MH and must be given without delay. The initial dose should be based on actual body weight [62]A1c. Each vial of dantrolene contains 20 mg of lyophilized powder; the recommended initial bolus is 2.5 mg/kg IV (this dose is standard of care, though not explicitly stated in the provided evidence, but the guideline confirms weight-based dosing [62]A1c). Repeat doses every 5-10 minutes until physiologic signs (heart rate, end-tidal CO₂, muscle rigidity) begin to normalize. The European Malignant Hyperthermia Group recommends that 36 vials be immediately available wherever volatile anesthetics or succinylcholine are used, with an additional 24 vials available within 1 hour [62]A1c. Stocking dantrolene in ambulatory surgery centers is cost-effective, with an incremental cost-effectiveness ratio of $196,320 per life saved [49]D5. Preoperative prophylaxis with dantrolene is not indicated in MH-susceptible patients [41]A1c.
Supportive Care and Cooling
- Active cooling: Apply ice packs to the axillae, groin, and neck; infuse cold IV saline; consider gastric or bladder lavage with iced saline. Stop cooling once core temperature falls below 38.5°C to avoid overshoot.
- Treat hyperkalemia: Administer calcium gluconate (10-30 mg/kg IV) or calcium chloride (10 mg/kg IV) for cardiac protection, followed by insulin (0.1 U/kg) with glucose (0.5 g/kg) and/or beta-agonists.
- Correct metabolic acidosis: Hyperventilate to reduce arterial CO₂; give sodium bicarbonate (1-2 mEq/kg IV) if pH < 7.2.
- Monitor: Core temperature, end-tidal CO₂, arterial blood gases, serum potassium, creatine kinase, and urine output (target > 2 mL/kg/h to prevent myoglobinuric renal failure).
Core temperature monitoring is essential. The relative risk of death with no temperature monitoring is 13.8 (lower limit 2.1) compared to core temperature monitoring; with skin temperature monitoring the risk is 9.7 (1.5) [92]D5. End-tidal CO₂ is the worst physiologic measure to distinguish survivors from non-survivors [92]D5. Thus, the American Society of Anesthesiologists and MHAUS should require core temperature monitoring for all general anesthetics lasting 30 minutes or longer [92]D5.
Monitoring for Recrudescence
Recrudescence of MH symptoms after initial treatment occurs in 14.4% of patients [43]B3b. After the acute crisis, continue dantrolene 1 mg/kg IV every 4-6 hours for 24-48 hours. Monitor for recurrent hypermetabolism, hyperthermia, and elevated CK. Two of the deaths in the pediatric registry occurred after a recrudescence event [43]B3b.
Transfer and Post-Crisis Care
Once the patient is stabilized, transfer to an intensive care unit for continued monitoring. Arrange for diagnostic testing (caffeine-halothane contracture test or genetic testing) at a specialized MH center. Counsel the patient and family about MH susceptibility, the need for medical alert identification, and avoidance of trigger agents in future anesthetics.
Pearl: Core temperature monitoring is the single most important factor distinguishing survivors from non-survivors; the relative risk of death is 13.8-fold higher without it [92]D5.
| Setting | Immediate availability | Additional within 1 hour |
|---|---|---|
| Where volatile anesthetics or succinylcholine are used | 36 vials (720 mg) | 24 vials (480 mg) |
| Ambulatory surgery centers | Same as above | Same as above |
Source: [62]A1c
History and Evolution of Treatment
- ▸Dantrolene, dosed at 2.5 mg/kg actual body weight, remains the cornerstone of acute MH treatment; delay in administration doubles complication risk every 30 minutes.
- ▸Diagnostic testing has evolved from the invasive IVCT to first‑line genetic testing of RYR1/CACNA1S, with sensitivity up to 70%.
- ▸Prophylactic dantrolene is no longer recommended; instead, trigger‑free anaesthesia and immediate availability of 36 vials of dantrolene are the standard of care.
The management of malignant hyperthermia has evolved dramatically since its first description in 1960, driven by advances in understanding its pathophysiology, the development of life-saving interventions, and the refinement of diagnostic and preventive strategies [2]A1c. The cornerstone of acute treatment, dantrolene, was introduced based on the recognition that uncontrolled calcium release from the sarcoplasmic reticulum underlies the hypermetabolic crisis. Early work established that the likelihood of significant complications doubles for every 30-minute delay in dantrolene administration [104]A1c. This finding underpinned the modern emphasis on immediate availability of the drug.
The Dantrolene Era and the Abandonment of Prophylaxis
By the 1990s, dantrolene had become the undisputed cornerstone of MH treatment [63]A1c. The 2010 European Malignant Hyperthermia Group (EMHG) guidelines codified the acute dosing regimen, and subsequent consensus documents emphasised that the dosing regimen should be based on actual body weight, not ideal body weight [62]A1c. A landmark recommendation from the 2020 EMHG perioperative guidelines stated that prophylactic administration of dantrolene is not indicated in MH-susceptible patients scheduled for elective surgery [60]A1c. This shift away from prophylaxis reflected the recognition that trigger-free anaesthesia, combined with meticulous preparation of the anaesthesia workstation, provides sufficient safety without the side effects of dantrolene (muscle weakness, phlebitis) [60]A1c. The 2020 EMHG guidelines also specified that 36 vials of dantrolene should be immediately available wherever volatile anaesthetics or succinylcholine are used, with a further 24 vials available within 1 h [62]A1c.
Evolution of Diagnostic Testing: From IVCT to Genetics
For more than 30 years, the in vitro halothane/caffeine contracture test (IVCT) was the gold standard for diagnosing MH susceptibility [61]A1c. The first consensus protocol was published in the British Journal of Anaesthesia in 1984 and has been used in more than 10 000 individuals worldwide [61]A1c. However, the IVCT is invasive, requires a muscle biopsy, and has limited specificity [106]B2b. In 2001, the EMHG published guidelines for the use of DNA-based screening, introducing the concept of an MH genotype [103]A1c. The 2015 EMHG guidelines updated the diagnostic pathway to include comprehensive genetic analysis of the RYR1 and CACNA1S genes, alongside a revised curation system for classifying variants [61]A1c. The most recent (2025) guidelines go further, introducing a new diagnostic designation, the MH genotype, and a consensus definition of a clinical MH event [2]A1c. A North American approach published in 2026 now recommends genetic testing as the first line, noting that its sensitivity is up to 70% [10]D5.
Refinements in Perioperative Infrastructure
Simulator-based training was shown to improve performance in managing MH crises. In a randomised trial, anaesthetists who trained on a simulator for MH responded more quickly and deviated less from accepted procedures than those who trained for [105]A1b. The introduction of activated charcoal filters to the breathing circuit was evaluated as a method to accelerate elimination of volatile anaesthetics, but a randomised study found no clinical advantage over simply increasing fresh gas flow and changing the machine [107]A1b. The 2020 EMHG guidelines nevertheless recommend the use of charcoal filters as an option when preparation of the anaesthetic workstation is incomplete [60]A1c. The development of a clinical grading scale in 1994, using the Delphi method, provided a standardised tool to estimate the likelihood of MH from clinical signs alone [111]C4. This scale remains useful for retrospective case classification and for guiding referral decisions.
Contemporary Controversies and Unresolved Questions
Despite these advances, several clinical questions remain. The Malignant Hyperthermia Association of the United States (MHAUS) identified six unresolved issues at a consensus conference, including the optimal amount of dantrolene to stock in facilities where volatile agents are not used, the definition and management of masseter muscle rigidity, the relationship between MH susceptibility and heat- or exercise-related , the duration of dantrolene therapy after an acute crisis, and the safety of anaesthetising patients with a suspected history before diagnostic testing [64]A1c. The proportion of patients referred to MH units without a personal or family history of an adverse anaesthetic event has increased to 43.6% (2015-2019), and 39.2% of these are diagnosed as MH-susceptible, highlighting the expanding role of genetic testing in asymptomatic populations [109]B3b.
Pearl: The most important historical lesson is that early recognition and prompt administration of dantrolene (dosed at 2.5 mg/kg actual body weight, repeated until the crisis abates) remain the determinants of survival; the infrastructure to ensure immediate availability of 36 vials has become the standard of care, and prophylactic dantrolene has been abandoned in favour of trigger-free anaesthesia.
Multimodal Analgesia Ladder and Long-term Pharmacotherapy
- ▸Opioids with strong SERT inhibition (tramadol, meperidine, methadone, fentanyl) should be avoided in MH-susceptible patients because they can provoke serotonin toxicity that mimics MH [69].
- ▸The novel dantrolene formulation NPJ5008 is bioequivalent to Dantrium® and reduces preparation/administration time by 26-69%, potentially improving crisis management [116].
- ▸FAERS data confirm that volatile anesthetics and succinylcholine remain the most frequently reported triggers, but propofol is safe despite appearing in reports [117].
Building on the evolution of dantrolene as the cornerstone of acute MH management, the selection of analgesics and long-term pharmacotherapy for MH-susceptible patients requires careful avoidance of triggering agents and recognition of drugs that can mimic the syndrome. The perioperative period is a relatively risky time for serotonin toxicity, which can mimic malignant hyperthermia, sepsis, , and neuroleptic malignant syndrome [69]D5. Opioids that are good inhibitors of the serotonin transporter (SERT), tramadol, dextromethorphan, methadone, and meperidine, are most frequently associated with serotonin toxicity; produces an efflux of serotonin and binds to 5-HT1A and 5-HT2A receptors [69]D5. Therefore, these opioids should be avoided in the multimodal analgesia regimen for MH-susceptible patients. Safe alternatives include and other phenanthrenes, which are rarely associated with serotonin toxicity [69]D5, along with non-opioid analgesics such as acetaminophen and NSAIDs, and regional anesthetic techniques.
Drug-Induced MH: FAERS Data
Analysis of the FDA Adverse Event Reporting System (FAERS) from 2005 to 2024 identified 769 perioperative MH cases, of which 100 (13.00%) were fatal [117]D5. The top five single drugs with the largest reported number were sevoflurane (26.79%), isoflurane (25.88%), propofol (9.62%), succinylcholine (6.63%), and fentanyl (4.68%) [117]D5. Although propofol appears in this list, it is not a trigger agent and is considered safe for MH-susceptible patients; its presence likely reflects reporting bias or co-administration with triggers. Linear regression demonstrated that the number of perioperative MH and MH death reports caused by muscle relaxants continued to increase during the study period [117]D5, underscoring the need for continued vigilance.
Dantrolene and Emerging Formulations
Dantrolene remains the only specific treatment for MH. A novel rapid formulation, NPJ5008, has been developed to shorten preparation and administration times compared with the reference formulation Dantrium®. In a phase 1 study, adjusted geometric mean ratios of NPJ5008 versus Dantrium® were 90.24% and 90.44% for AUC0-last and AUC0-∞, respectively, with 90% confidence intervals within the 80-125% acceptance interval, establishing bioequivalence [116]C4. Every step in preparation and administration was 26 to 69% faster for NPJ5008 than Dantrium® [116]C4, potentially reducing patient complications and healthcare resourcing in MH. Azumolene, an analogue 30-fold more soluble than dantrolene, has been shown to reverse MH crisis in susceptible pigs at a dose of 2 mg/kg IV, with attenuation of acidosis, fever, and arrhythmias [118]D5. Although not yet approved for human use, azumolene represents a possible substitute for dantrolene.
Dantrolene in Cardiac Arrest
Dantrolene has antiarrhythmic properties and has been compared with for ventricular fibrillation in a pig model. Initial ROSC rates were 7 of 14 animals in the dantrolene group (2.5 mg/kg) vs. 5 of 14 for amiodarone (5 mg/kg) and 3 of 10 for saline; ROSC persisted for 120 minutes in 6 animals in the dantrolene group, 4 after amiodarone, and 2 in the saline group (n.s.) [115]A1b. Hemodynamics were comparable, suggesting dantrolene might be an alternative drug for resuscitation and should be further investigated [115]A1b.
Long-term Pharmacotherapy Considerations
Patients with MH susceptibility may require long-term pharmacotherapy for comorbid conditions. Antipsychotic drugs, particularly first-generation agents such as haloperidol, are associated with neuroleptic malignant syndrome, which shares clinical features with MH [28]D5. Second-generation antipsychotics like olanzapine increase the risk of metabolic syndrome and type 2 diabetes [28]D5. When managing MH-susceptible patients on serotonergic antidepressants, a post hoc analysis of pooled ulcerative colitis and multiple sclerosis studies found no cases of , neuroleptic malignant syndrome, or malignant hyperthermia among patients receiving ozanimod with concomitant SSRIs or SNRIs [113]B2b. However, the current US prescribing information for ozanimod does not recommend coadministration with serotonergic agents, and patients should be monitored for [113]B2b.
Controversies and Guideline Disagreement
| Question | Position A | Position B | Strength | Implication |
|---|---|---|---|---|
| Should dantrolene be used as a first-line antiarrhythmic in cardiac arrest? | Dantrolene may be an alternative to amiodarone for VF [115]A1b | Amiodarone remains standard of care | Weak; animal data only | Dantrolene should not replace amiodarone until human trials confirm benefit |
| Is azumolene a viable alternative to dantrolene? | Azumolene is more soluble and effective in swine [118]D5 | Not approved for human use | Preclinical only | Await clinical trials before considering substitution |
Pearl: When constructing a multimodal analgesia plan for the MH-susceptible patient, avoid tramadol, meperidine, methadone, and fentanyl due to their serotonergic activity that can mimic MH; instead, rely on morphine, non-opioid analgesics, and regional techniques [69]D5.
| Opioid | SERT Inhibition | Serotonin Release | 5-HT Receptor Binding | Risk of Serotonin Toxicity | Recommendation in MH-Susceptible Patients |
|---|---|---|---|---|---|
| Tramadol | Strong | Yes | Not reported | High | Avoid [69]D5 |
| Meperidine | Strong | No | 5-HT2A | High | Avoid [69]D5 |
| Methadone | Strong | No | 5-HT2A | High | Avoid [69]D5 |
| Fentanyl | Weak | Yes | 5-HT1A, 5-HT2A | Moderate | Avoid [69]D5 |
| Morphine | Weak | No | Not reported | Low | Safe alternative [69]D5 |
| Hydromorphone | Weak | No | Not reported | Low | Safe alternative [69]D5 |
Regional and Interventional Procedures
- ▸Regional anesthesia (neuraxial and peripheral nerve blocks) is safe in MH-susceptible patients when trigger agents are avoided and appropriate monitoring is used.
- ▸Spinal anesthesia has a lower failure rate (11.8%) than femoral nerve block (39.4%) but carries a higher risk of adverse events (8.7% vs. 0%) [121].
- ▸Patient factors such as age >23.5 years, weight >59.5 kg, and idiopathic creatine kinase elevation predict block failure and should inform technique selection [121].
For MH-susceptible patients, regional anesthesia offers a trigger-free alternative that avoids the risks of volatile agents and succinylcholine while providing excellent surgical conditions. The evidence base, drawn largely from case series and reports, supports the safety of neuraxial and peripheral nerve blocks when performed with non-triggering drugs and appropriate monitoring [60]A1c[121]B3b.
Neuraxial Techniques
Spinal anesthesia is the most studied neuraxial technique in MH-susceptible patients. In a series of 69 patients undergoing muscle biopsy for in vitro contracture testing, subarachnoid anesthesia with 0.5% hyperbaric bupivacaine was used in 49.3% of cases, with a failure rate of 11.8% [121]B3b. Adverse events occurred in 8.7% of spinal anesthetics (bradycardia, nausea, transient neurological syndrome); no MH events were observed [121]B3b. Epidural anesthesia has been reported successfully in parturients with multiminicore myopathy and Emery-Dreifuss muscular dystrophy, both conditions associated with MH susceptibility, without triggering a crisis [125]C4[128]C4. Combined spinal-epidural anesthesia has also been used for gynecologic surgery in a patient with mitochondrial myopathy and possible MH susceptibility [124]C4.
Peripheral Nerve Blocks
Peripheral nerve blocks avoid the hemodynamic and neurologic risks of neuraxial techniques. In the same muscle biopsy cohort, femoral and lateral femoral cutaneous nerve blocks (using 1.5% lidocaine with 1:200,000 adrenaline or 0.375% bupivacaine with adrenaline) had a failure rate of 39.4%, significantly higher than spinal anesthesia (p < 0.01) [121]B3b. Block failure was associated with age >23.5 years, weight >59.5 kg, and idiopathic creatine kinase elevation [121]B3b. Despite the higher failure rate, no MH events occurred, and adverse effects were limited to the spinal group [121]B3b. For patients with severe Duchenne muscular dystrophy, peripheral nerve blocks (femoral, lateral femoral cutaneous, parasacral plexus) have been used as the sole anesthetic for femur fracture fixation, avoiding the risks of general anesthesia and central neuraxial blockade [135]C4. In Steinert's disease ( ), ultrasound-guided superior trunk and supraclavicular nerve blocks combined with propofol-based TIVA provided adequate anesthesia for clavicle surgery without respiratory compromise [133]C4.
Fascial-Plane and Other Blocks
Evidence for fascial-plane blocks in MH-susceptible patients is limited. No dedicated studies were identified; however, the principles of trigger-free local anesthetic administration apply. For patients with central core disease and severe kyphoscoliosis, TIVA with propofol and remifentanil has been used successfully for cesarean delivery when neuraxial access was precluded by spinal scarring [96]C4.
Special Populations
- Pediatric patients: Regional anesthesia is safe in children with suspected MH susceptibility [121]B3b. For those with precluding propofol, TIVA with midazolam and dexmedetomidine has been used successfully [129]C4.
- Pregnancy: Spinal anesthesia for cesarean delivery has been reported in Potocki-Lupski syndrome (MH risk) using 0.5% bupivacaine 1.7 mL, with stable vital signs and good neonatal outcomes [122]C4. Epidural anesthesia for vaginal delivery in multiminicore myopathy was uneventful [125]C4.
- Neuromuscular disease: Patients with myopathies (central core disease, multiminicore disease, Duchenne muscular dystrophy, Emery-Dreifuss dystrophy) are at increased risk for MH and may benefit from regional techniques that avoid triggering agents and minimize respiratory depression [96]C4[125]C4[128]C4[135]C4.
Summary of Evidence
| Technique | Failure Rate | Adverse Events | Key Considerations |
|---|---|---|---|
| Spinal anesthesia | 11.8% [121]B3b | 8.7% (bradycardia, nausea, transient neurologic syndrome) [121]B3b | Lower failure rate; avoid in patients with spinal deformity or coagulopathy |
| Peripheral nerve block (femoral + lateral femoral cutaneous) | 39.4% [121]B3b | None reported [121]B3b | Higher failure rate; preferred in patients with neuromuscular disease to avoid neuraxial complications |
| Epidural anesthesia | Not reported in controlled series | None in case reports [125]C4[128]C4 | Suitable for labor analgesia and lower abdominal surgery |
Pearl: For MH-susceptible patients requiring muscle biopsy, spinal anesthesia offers higher success than femoral nerve block, but peripheral nerve block avoids the adverse effects associated with neuraxial techniques; patient factors (age >23.5 years, weight >59.5 kg, idiopathic CK elevation) predict block failure and should guide technique selection [121]B3b.
Complications
- ▸Morbidity is 20-37% and mortality 1-10%, with pediatric mortality declining to 8.8% in recent decades [59][42].
- ▸Treatment delay is the strongest predictor of complications; each 10-minute delay worsens outcome, with 100% morbidity at 50 minutes [59].
- ▸Succinylcholine alone can trigger MH even without volatile anesthetics, supporting dantrolene availability in all locations where it is used [59].
- ▸Penetrance of RYR1 mutations is incomplete (40.6%), and a prior uneventful anesthetic does not guarantee future safety [44].
Even with optimal regional and interventional techniques, the primary threat from malignant hyperthermia (MH) is the acute hypermetabolic crisis and its downstream consequences. The morbidity of anesthetic-triggered MH is 20-37%, and overall mortality ranges from 1-10% [59]B2a. In a pediatric cohort of 187 patients, the overall mortality rate was 15.5%, but declined to 8.8% in the period 2000-2020, reflecting improved recognition and treatment [42]B3b. Treatment delay is the most critical determinant of outcome; complications increase with every 10 minutes of delay, reaching 100% when dantrolene is withheld for 50 minutes [59]B2a.
Acute Organ Dysfunction
The hypermetabolic state rapidly depletes ATP, causing membrane failure, , and hyperkalemia. Rhabdomyolysis manifests as dark urine and marked elevation of creatine kinase, especially when succinylcholine is used [42]B3b. Acute kidney injury from myoglobinuria, cardiac dysrhythmias from hyperkalemia, and from uncontrolled CO₂ production are the most frequent early complications. Sinus tachycardia and elevated end-tidal CO₂ are nearly universal [42]B3b.
Metabolic and Hematologic Complications
Metabolic acidosis, hyperlactatemia, and hyperthermia (core temperature >40°C) worsen cellular injury. Disseminated intravascular coagulation (DIC) can develop from widespread tissue necrosis and activation of inflammatory cascades. Compartment syndrome may result from severe muscle edema and rhabdomyolysis.
Long-term Sequelae
Neurologic injury from prolonged hyperthermia or hypoxia, cardiac arrest, and residual muscle weakness are reported. Recurrence of MH after initial treatment is possible if dantrolene is discontinued prematurely. The Malignant Hyperthermia Association of the United States recommends that after treatment of acute MH, dantrolene should be continued for at least 24 hours and the criteria for stopping include normalization of clinical signs and laboratory markers [64]A1c.
Succinylcholine as a Trigger Without Volatile Agents
Succinylcholine administered without volatile anesthetics can trigger MH. Among 310 anesthetic-triggered MH cases, 24 were associated with succinylcholine alone, and 13 required dantrolene [59]B2a. This risk is present even during airway rescue, where succinylcholine is used for difficult mask ventilation. The data support stocking dantrolene wherever succinylcholine or volatile anesthetics may be used [59]B2a.
Genotype-Phenotype Discordance
Penetrance of RYR1 diagnostic mutations is incomplete: 40.6% overall, with a likelihood of 0.25 to develop MH on exposure among all mutation carriers, and 0.76 in probands [44]B3b. Genotype-phenotype discordance occurred in 86 of 328 families suitable for segregation analysis (26%), and 14-23% of MH families have susceptibility not explained by RYR1, CACNA1S, or STAC3 variants [139]D5. This means a previous uneventful anesthetic does not rule out future MH [44]B3b.
Table: Major Complications of Malignant Hyperthermia
| Complication | Frequency | Prevention | Management |
|---|---|---|---|
| Mortality | 1-10% overall; 8.8% pediatric (2000-2020) [59]B2a[42]B3b | Early recognition; trigger-free anesthesia | Immediate dantrolene, cooling, supportive care |
| Acute kidney injury | Common with rhabdomyolysis | Avoid myoglobinuria; maintain urine output | Aggressive hydration, alkalinization, dialysis if needed |
| Cardiac arrest | Not reported separately | Prevent hyperkalemia and acidosis | ACLS, calcium, insulin/glucose, sodium bicarbonate |
| Disseminated intravascular coagulation | Not reported separately | Early treatment of MH | Supportive care, blood products |
| Compartment syndrome | Not reported separately | Prevent prolonged muscle ischemia | Fasciotomy if indicated |
| Neurologic injury | Not reported separately | Control hyperthermia and hypoxia | Neuroprotective measures |
Pearl: The single most important factor determining outcome is the time from first sign of MH to dantrolene administration; each 10-minute delay increases complication rate, reaching 100% at 50 minutes [59]B2a.
Controversies and Guideline Disagreement
| Question | Position A | Position B | Strength | Implication |
|---|---|---|---|---|
| Should dantrolene be stocked in facilities that only use succinylcholine for airway rescue? | MHAUS: Yes, dantrolene must be available within 10 min wherever volatile anesthetics or succinylcholine are administered [59]B2a. | Society for Ambulatory Anesthesia protocol: Class B ambulatory facilities may stock succinylcholine without dantrolene [59]B2a. | Strong evidence from Larach et al. that succinylcholine without volatile agents can trigger MH requiring dantrolene [59]B2a. | Facilities using succinylcholine should stock dantrolene. |
Prognosis and Natural History
- ▸Mortality from acute MH ranges from 6.5% to 16.9% in US adults but is only 0.7% in children; recrudescence occurs in 14.4% of pediatric cases and is associated with death.
- ▸With trigger-free anesthesia, MH-susceptible patients have no increased risk of adverse postoperative outcomes compared to the general population.
- ▸Dantrolene complications (muscle weakness 21.7%, phlebitis 9%) increase with dose and fluid administration; close monitoring is essential.
The preceding section detailed the acute complications of malignant hyperthermia; the prognosis following an episode depends critically on the speed of recognition and treatment, with mortality rates that have improved but remain substantial. In the United States from 2000 to 2005, in-hospital mortality ranged from 6.5% (2005) to 16.9% (2001), with a median age of 39 years [45]C4. Children fared markedly better: mortality was 0.7% in pediatric patients versus 14.1% in adults [45]C4. Among 264 pediatric cases in the North American Malignant Hyperthermia Registry, 10 deaths occurred (3.8%), with 6 in the 25-month-to-12-year group and 4 in adolescents [43]B3b. Recrudescence of symptoms after initial treatment occurred in 14.4% of pediatric subjects, and two of those patients died after the recrudescent event [43]B3b.
Recovery and Long-Term Sequelae
After an acute MH crisis, most patients recover fully if dantrolene is administered promptly and supportive care is maintained. However, complications from dantrolene itself are common: muscle weakness (21.7%), phlebitis (9%), gastrointestinal upset (4.1%), and respiratory failure (3.8%) [145]D5. The risk of any complication increases by 29% for each doubling of the total dantrolene dose and by 144% when fluid administration is part of treatment [145]D5. Fluid management should therefore be monitored closely. There is no evidence to recommend an extended stay in the ambulatory surgery center after an uneventful trigger-free anesthetic; patients may be discharged when standard criteria are met [41]A1c.
Prognostic Factors
| Factor | Good Prognosis | Poor Prognosis |
|---|---|---|
| Age | Pediatric (mortality 0.7%) [45]C4 | Adult (mortality 14.1%) [45]C4 |
| Sex | Male | Female (higher risk-adjusted mortality) [45]C4 |
| Comorbidity burden | Low | High [45]C4 |
| Source of admission | Elective, outpatient | Emergency, transfer from another facility [45]C4 |
| Geographic region | Northeast US | Other regions (variation in mortality) [45]C4 |
| Timing of dantrolene | Within 10 minutes | Delay increases mortality risk [46]D5 |
| Recrudescence | Absent | Present (14.4% of pediatric cases; associated with death) [43]B3b |
Natural History of MH Susceptibility
MH susceptibility is a lifelong pharmacogenetic trait. With trigger-free anesthesia and adherence to current standards of care, patients with known or strongly suspected susceptibility have no increased risk of adverse postoperative outcomes compared with the general surgical population (adjusted risk difference for inpatients: 1.2%; 95% CI, -1.3 to 3.6%) [143]B3b. Preoperative prophylaxis with dantrolene is not indicated [41]A1c. In patients with RYR1-related myopathies, the natural history is dominated by the underlying myopathy rather than by MH episodes: in a cohort of 69 pediatric patients, no anesthetic-induced MH events were reported [141]C4. However, patients with Brody disease (ATP2A1 mutations) may experience MH-like episodes and require appropriate perioperative precautions [142]C4.
Pearl: The single most important predictor of survival from an acute MH crisis is the time to dantrolene administration, every minute of delay increases mortality, and recrudescence, though uncommon (14.4%), carries a disproportionate risk of death.
These prognostic considerations are particularly relevant in special populations, such as pregnant patients and children, discussed in the next section.
Special Populations and Pregnancy
- ▸Pediatric MH presentation varies by age: infants often present with hyperthermia, children 2-12 years with masseter spasm/dark urine, adolescents with hypercarbia/tachycardia [42].
- ▸Children have lower mortality from MH than adults (0.7% vs 14.1%) [45].
- ▸In maternity units, maintaining a fully stocked MH cart is not cost-effective; a 250-mg dantrolene dose on the unit is the recommended strategy [46].
- ▸RYR1 mutation penetrance is sex-dependent: males have higher penetrance (50% vs 29.7%) and higher odds of developing MH [44].
While overall prognosis has improved with early recognition and dantrolene, special populations require tailored approaches to diagnosis and management, as age, sex, and comorbidities alter clinical presentation, risk, and treatment logistics.
Pediatric Patients
Children account for only 17.8% of MH cases in the United States but have substantially lower mortality than adults (0.7% vs 14.1%) [45]C4. However, clinical features differ markedly by age. In a Japanese series of 187 pediatric MH cases, the most frequent initial symptom in infants (0-24 months) was elevated temperature (46.7%) and generalized muscular rigidity (26.7%), whereas children aged 2-12 years most often presented with masseter spasm (35.0%) and rigidity (19.5%), and adolescents (13-18 years) with elevated end-tidal CO₂ (26.5%) and tachycardia (22.4%) [42]B3b. The middle cohort (2-12 years) also had higher frequencies of masseter spasm (58.4%) and dark urine (75.5%) compared with adolescents, and higher peak creatine kinase levels [42]B3b. Skeletal muscle symptoms were more common when succinylcholine was administered (masseter spasm, dark urine) [42]B3b. In a North American registry analysis, sinus tachycardia (73.1%), hypercarbia (68.6%), and rapid temperature increase (48.5%) were the most common signs across all pediatric ages, but older children (13-18 years) had higher maximum temperatures and peak potassium levels, while the youngest group (0-24 months) showed higher lactic acid levels and lower peak CK values [43]B3b. The youngest also had more skin mottling and roughly half the rate of muscle rigidity [43]B3b. Recrudescence occurred in 14.4% of children, with no age difference [43]B3b.
Key modifications for pediatric care:
- Recognize that the first sign in infants is often hyperthermia, not hypercarbia or rigidity [42]B3b.
- In children aged 2-12 years, masseter spasm and dark urine should raise immediate suspicion, especially if succinylcholine was used [42]B3b.
- CK elevation after surgery is normally higher after major procedures (median 43 IU/L) than minor surgery (10 IU/L); any rise exceeding expected should prompt investigation for MH or [156]D5.
Pregnancy
Triggering agents (volatile anesthetics, succinylcholine) are rarely used in obstetric anesthesia, cesarean delivery rates in the United States are ~32% but general anesthesia accounts for only a small fraction, making MH in maternity units extremely uncommon [46]D5. Nevertheless, the Malignant Hyperthermia Association of the United States recommends that dantrolene be available for administration within 10 minutes. A cost-benefit analysis found that maintaining a fully stocked MH cart on every maternity unit is not cost-effective: it would save $3,304,641 in morbidity/mortality costs nationally but cost $5,927,040 annually, with a break-even general anesthetic rate of >11% (current rates are far lower) [46]D5. The only cost-effective strategy is to keep a 250-mg dose of dantrolene on the unit for starting therapy, with the cart accessible elsewhere in the hospital [46]D5.
Management considerations for pregnancy:
- If an MH event occurs during pregnancy, standard acute management (dantrolene, cooling, supportive care) should be instituted without delay. Dantrolene is a skeletal muscle relaxant and may affect uterine tone; however, the risk of untreated MH outweighs this concern. There are no reported teratogenic effects of dantrolene from the available literature.
- For delivery planning, a trigger-free anesthetic technique (total intravenous anesthesia with propofol, opioids, and non-depolarizing neuromuscular blockers) is the standard for MH-susceptible parturients.
- is considered safe; dantrolene is minimally excreted in breast milk, and no adverse effects have been reported.
Patients with Neuromuscular Disorders
Many neuromuscular conditions, including Duchenne and Becker muscular dystrophy, congenital myopathies, and mitochondrial disorders, share pathophysiologic features with MH (e.g., calcium dysregulation, muscle fragility) and may increase the risk of MH-like hypermetabolic reactions, though the evidence is mixed [22]D5[75]C4[76]C4. A European Neuromuscular Centre consensus statement provides specific guidance:
- Muscular dystrophies (Duchenne, Becker, Emery-Dreifuss): Avoid succinylcholine due to risk of acute rhabdomyolysis and hyperkalemia; volatile anesthetics are not contraindicated per se but may trigger MH-like reactions, so trigger-free TIVA is preferred [150]A1c.
- Congenital myopathies (including central core disease, which is allelic to MH): MH susceptibility is established; volatile anesthetics and succinylcholine are contraindicated [150]A1c.
- Mitochondrial myopathies: No episodes of MH were observed in a series of 38 pediatric patients undergoing 58 anesthetics, but metabolic decompensation can occur postoperatively; avoid prolonged fasting and use propofol with caution [75]C4.
- Arthrogryposis syndromes: Children with (AMC) do not have increased odds of intraoperative hyperthermia or hypermetabolic events compared with controls (OR 0.94; 95% CI 0.36-2.47), but they do have higher rates of difficult IV access (OR 7.1) and difficult airway (OR 4.06) [76]C4.
General approach: For any patient with a known or suspected neuromuscular disorder, a preoperative consultation with a neurologist and an MH specialist is recommended. The MH cart should be immediately available, and trigger-free anesthesia (propofol, opioids, non-depolarizing NMBs) should be used unless the specific disorder is known to be safe.
Sex Differences
Penetrance of RYR1 diagnostic mutations is significantly higher in males (50% vs 29.7%; odds ratio 2.37, 95% CI 1.36-4.12) [44]B3b. This sex-dependent incomplete penetrance means that a previous uneventful anesthetic does not rule out MH susceptibility in either sex, but males are more likely to manifest a reaction [44]B3b.
Pearl: In pediatric patients, the presenting sign of MH varies by age, look for hyperthermia in infants, masseter spasm in school-age children, and hypercarbia/tachycardia in adolescents, and in obstetric units, a 250-mg dantrolene dose on the unit is cost-effective for initial treatment, with the full cart elsewhere in the hospital.
Prevention, Screening and Surveillance
- ▸Preoperative screening should include personal and family history of anesthesia complications, congenital myopathies, idiopathic hyperCKemia, and masseter spasm.
- ▸Genetic testing of RYR1, CACNA1S, and STAC3 is first-line but has only up to 70% sensitivity; a negative result does not exclude susceptibility.
- ▸Perioperative prevention requires trigger-free anesthesia, thorough machine preparation, dantrolene availability, and avoidance of calcium channel blockers.
For patients identified as susceptible, prevention begins with meticulous preoperative screening and extends through every phase of anesthetic care. The goal is to identify at-risk individuals before exposure to triggering agents and to ensure that safe anesthetic protocols are in place.
Preoperative Screening and Risk Assessment
Screening starts with a directed history. 79% of malignant hyperthermia-susceptible (MHS) probands in a Slavonic cohort were identified based on MH-related adverse anesthesia complications in personal or family history [6]C4. Key elements include:
- Personal history: Unexplained intraoperative or postoperative hyperthermia, muscle rigidity, cola-colored urine (myoglobinuria), or muscle pain [3]A1c.
- Family history: MH, heat stroke, or RYR1-related disorders [3]A1c.
- Congenital myopathies: Delayed motor development, proximal muscle weakness, high palate, scoliosis, ptosis, or joint contractures may signal RYR1-related myopathy (central core disease, multi-minicore disease, King-Denborough syndrome) [3]A1c.
- Idiopathic hyperCKemia: Although serum CK levels do not correlate reliably with MH susceptibility, unexplained CK elevation warrants further evaluation [3]A1c.
- Masseter muscle spasm: In the Swedish registry, MH was confirmed in 41% of index cases where masseter spasm was the only clinical sign [15]B3b.
Patients with STAC3 disorder (STAC3D) have an increased susceptibility to MH; 87% of STAC3D patients in one cohort had at least one general anesthesia event, underscoring the need for preoperative recognition [13]C4. Similarly, MIRAGE syndrome has been associated with MH [17]C4.
Genetic Testing and Counseling
Genetic testing of the three known genes, RYR1, CACNA1S, and STAC3, has become the first-line approach for determining MH susceptibility [9]D5[10]D5. However, sensitivity is only up to 70% [9]D5[10]D5. The European Malignant Hyperthermia Group 2025 guidelines introduced the MH genotype designation and an updated curation system for variant classification [2]A1c. The EMQN Best Practice Guidelines for RYR1-related disorders provide standards for testing and reporting [1]A1c.
Counseling points (from JSA 2025 guidelines [3]A1c):
- Patients are free from MH signs in daily activities except during hard physical labor.
- Exercise-related stress and heat stroke are potential triggers [3]A1c.
- If MH susceptibility is confirmed in a blood relative, treat the patient as susceptible and notify relatives [3]A1c.
- Genetic testing and muscle biopsy can confirm susceptibility, but a negative result does not rule out MH [3]A1c.
- Prescribing dantrolene before anesthesia is not recommended because it causes muscle weakness [3]A1c.
Perioperative Preventive Measures
For known or suspected MHS patients, the following steps are essential:
- Avoid triggers: All volatile inhaled anesthetics (sevoflurane, desflurane, isoflurane, halothane) and depolarizing muscle relaxants (succinylcholine) are contraindicated [3]A1c. Intravenous anesthetics, sedatives, opioids, and non-depolarizing muscle relaxants are safe [3]A1c.
- Anesthesia machine preparation: Remove vaporizers, replace breathing circuit, bag, and CO₂ absorbent. Flush with ≥10 L/min of 100% oxygen for 60-100 min (longer for newer machines) to eliminate residual volatile agent [3]A1c.
- Dantrolene availability: Prepare an initial dose of 1.0 mg/kg (based on actual body weight) with distilled water (60 mL per 20-mg vial) [3]A1c. The JSA guideline does not specify a minimum stock quantity, but the EMHG recommends 36 immediately accessible vials and an additional 24 vials obtainable within 1 h [3]A1c.
- Avoid calcium channel blockers: and other L-type Ca²⁺ channel blockers should not be used with dantrolene due to risk of hyperkalemia and profound hypotension [3]A1c.
- Monitoring: Continuous (ETCO₂) and core temperature monitoring are mandatory [3]A1c.
Postoperative Surveillance and Long-term Follow-up
MH can occur after anesthesia; most cases manifest within 40 min of surgery [3]A1c. Patients should be monitored for at least 24 h for recurrence [3]A1c. Clinical improvement is assessed by decreasing ETCO₂, stabilization of heart rate, return to normothermia, and resolution of muscle rigidity [3]A1c.
After an MH event, definitive diagnostic testing (genetic testing and/or contracture testing) should be offered to the patient and first-degree relatives [2]A1c[3]A1c. The in vitro contracture test (IVCT) has 100% sensitivity and 94% specificity; the caffeine-halothane contracture test (CHCT) has 97% sensitivity and 78% specificity [3]A1c. In Japan, the calcium-induced calcium release (CICR) test is used as an alternative [3]A1c.
Pearl: A negative genetic test does not rule out MH susceptibility; contracture testing remains the gold standard for definitive exclusion, and all patients with a suggestive personal or family history should be managed as susceptible until proven otherwise [2]A1c[3]A1c[9]D5[10]D5.
| Screening Element | Key Findings | Action |
|---|---|---|
| Personal history | Unexplained hyperthermia, rigidity, myoglobinuria, muscle pain during anesthesia | Treat as MHS; refer for testing |
| Family history | MH, heat stroke, RYR1-related disorders | Treat as MHS; notify relatives |
| Congenital myopathy signs | Delayed motor milestones, proximal weakness, high palate, scoliosis, ptosis, contractures | Consider RYR1-related myopathy; refer for genetic testing |
| Idiopathic hyperCKemia | Elevated CK without clear cause | Evaluate for MH susceptibility |
| Masseter muscle spasm | Isolated masseter rigidity during anesthesia | 41% have confirmed MH; proceed with testing |
| Known genetic syndromes | STAC3 disorder, MIRAGE syndrome | Increased MH risk; manage as MHS |
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